Severe valgus deformity of the knee with permanent patellar dislocation associated with melorheostosis: A case report and review of the literature

Yuki Kitta, Yasuo Niki, Kazuhiko Udagawa, Hiroyuki Enomoto, Yoshiaki Toyama, Yasunori Suda

Research output: Contribution to journalArticle

7 Citations (Scopus)

Abstract

We present a case of an 8-year-old boy diagnosed with melorheostosis who was suffering from severe genu valgum, permanent dislocation of the patella, knee flexion contracture and leg length shortening. Soft tissue contracture of the limb and subsequent joint deformities were reported to represent clinical manifestations of pediatric melorheostosis. As the epiphyseal plate had not closed, patellar reduction was achieved by soft tissue surgical stabilization, including lateral retinacular release, medial retinaculum plication, and transfer of the lateral half of the patellar tendon. At 4. years postoperatively, as a result of improved limb alignment and knee flexion contracture, the leg length shortening has improved, and the patient does not limp and participates in sports activities. Surgical intervention should be performed as early as possible, because genu valgum and external rotation of the tibia may deteriorate with age, rendering the patellar dislocation irreversible in patients with melorheostosis before epiphyseal closure.

Original languageEnglish
Pages (from-to)589-593
Number of pages5
JournalKnee
Volume21
Issue number2
DOIs
Publication statusPublished - 2014

Fingerprint

Melorheostosis
Patellar Dislocation
Contracture
Genu Valgum
Knee
Leg
Extremities
Knee Dislocation
Patellar Ligament
Growth Plate
Patella
Tibia
Sports
Joints
Pediatrics

Keywords

  • Ectopic ossification
  • Melorheostosis
  • Patellar dislocation
  • Soft tissue contracture
  • Valgus deformity of the knee

ASJC Scopus subject areas

  • Orthopedics and Sports Medicine
  • Medicine(all)

Cite this

Severe valgus deformity of the knee with permanent patellar dislocation associated with melorheostosis : A case report and review of the literature. / Kitta, Yuki; Niki, Yasuo; Udagawa, Kazuhiko; Enomoto, Hiroyuki; Toyama, Yoshiaki; Suda, Yasunori.

In: Knee, Vol. 21, No. 2, 2014, p. 589-593.

Research output: Contribution to journalArticle

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